Documentation of Spontaneous Macular Hole Closure in Macular Telangiectasia Type 2 Using Multimodal Imaging

Purpose: To describe a case of macular telangiectasia type 2 (MacTel) presenting with decreased vision due to intraretinal/sub-internal limiting membrane (ILM) hemorrhage in the absence of neovascularization. Method: Clinical examination and multimodal imaging were performed. Results: A 65-year-old female presented with blurred left vision, recording 20/160 in that eye. There was intraretinal hemorrhage at the left macula centrally, with sub-ILM hemorrhage superiorly and inferiorly. Optical coherence tomography (OCT) showed no evidence of subretinal neovascularization. Imaging of the right macula was consistent with MacTel. The blood spontaneously cleared and the left visual acuity gradually improved to 20/25 by 4 months. Fluorescein angiography confirmed MacTel, and once the hemorrhage resolved, both inner and outer retinal cavitation was identified on OCT of the left macula. The left best-corrected visual acuity remained at 20/25 at 2-year follow-up. Conclusion: Spontaneous resorption of hemorrhage was accompanied by visual improvement.

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Idiopathic macular telangiectasia type 2, stage V or proliferative stage: Multimodal imaging

Journal Français d Ophtalmologie ◽

10.1016/j.jfo.2021.02.020 ◽

2021 ◽

Author(s):

J.L. Sánchez-Vicente ◽

J. de las Morenas-Iglesias ◽

B. González-Jáuregui-López ◽

T. Rueda-Rueda ◽

Á. Espiñeira-Periñán ◽

...

Keyword(s):

Multimodal Imaging ◽

Macular Telangiectasia ◽

Proliferative Stage ◽

Macular Telangiectasia Type 2 ◽

Idiopathic Macular Telangiectasia

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Spontaneous Closure of a Macular Hole in Macular Telangiectasia Type 2

Journal of VitreoRetinal Diseases ◽

10.1177/2474126420958907 ◽

2020 ◽

pp. 247412642095890

Author(s):

Varun Chandra ◽

Rohan Merani ◽

Alex P. Hunyor ◽

Mark Gillies

Keyword(s):

Macular Hole ◽

Internal Limiting Membrane ◽

Spontaneous Closure ◽

Full Thickness ◽

External Limiting Membrane ◽

Macular Telangiectasia ◽

History Of ◽

Macular Telangiectasia Type 2 ◽

The Right

Purpose: Spontaneous closure of a macular hole in macular telangiectasia type 2 (MacTel) with vision improvement is described. Methods: A case report is presented. Results: A 71-year-old man presented with a 1-week history of distorted vision in his left eye. Left visual acuity (LVA) was 20/80. Optical coherence tomography showed an almost full-thickness left macular hole with an intact internal limiting membrane drape. Small inner retinal cavitations were present at the right macula; multimodal imaging confirmed MacTel. Managed conservatively, at 5 months the patient’s LVA had improved to 20/60, the defect was no longer full thickness, and the external limiting membrane had reconstituted. At the right macula, the inner cavitations grew and outer cavitations developed, but the external limiting membrane remained intact. At 32 months, right VA was 20/20 and LVA was 20/40. Conclusions: This case of MacTel with spontaneous closure of a macular hole was associated with an overlying internal limiting membrane drape.

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