A rare case of coexisting left pulmonary hypoplasia and right tracheal bronchus

Pulmonary hypoplasia is a bronchopulmonary foregut anomaly in which gross morphology of the lung is preserved but there is decrease in the number or size of airways, vessels, and alveoli. Unilateral pulmonary hypoplasia is a rare clinical condition and most patients reported in the literature are newborns and infants, but patients may remain asymptomatic until late adolescent or till adulthood 65 years old male with parkinsonism was referred to our department with complaints of recent chest symptoms. Clinical examination revealed loss of lung volume in left hemithorax. CT scan thorax and bronchoscopy confirmed the diagnosis of left sided pulmonary hypoplasia. This case report highlights the possibility of pulmonary hypoplasia as one of the differential diagnoses in adult patients presenting with loss of lung volume and to the best of our knowledge he is the eldest patient so far reported.

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A Rare Case of a Tracheal Bronchus

The Journal of Association of Chest Physicians ◽

10.4103/jacp.jacp_28_17 ◽

2018 ◽

Vol 6 (2) ◽

pp. 76

Author(s):

Arpit Jain ◽

RaviA Dosi ◽

Prakash Joshi ◽

Satish Motiwale ◽

Ashwin Songara

Keyword(s):

Rare Case ◽

Tracheal Bronchus

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A rare case of displaced tracheal bronchus as a cause of recurrent bronchitis and cystic bronchiectasis in an adult patient

Journal of Radiological Review ◽

10.23736/s2723-9284.20.00023-4 ◽

2020 ◽

Vol 7 (3) ◽

Author(s):

Anna SIKORA ◽

Valentina SETTINO ◽

Maria PETULLÀ ◽

Anna ROTUNDO ◽

Francesco MANTI ◽

...

Keyword(s):

Adult Patient ◽

Rare Case ◽

Tracheal Bronchus

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A Singleton Infant with Bilateral Renal Agenesis and Normal Pulmonary Function

Case Reports in Pediatrics ◽

10.1155/2017/1710371 ◽

2017 ◽

Vol 2017 ◽

pp. 1-3

Author(s):

Lovya George ◽

Winston Manimtim ◽

Jotishna Sharma

Keyword(s):

Peritoneal Dialysis ◽

Pulmonary Function ◽

Rare Case ◽

Pulmonary Hypoplasia ◽

Renal Agenesis ◽

Neonatal Period ◽

Case Reports ◽

Singleton Pregnancy ◽

First Case ◽

Discordant Twins

Bilateral renal agenesis leads to anhydramnios and other sequelae including pulmonary hypoplasia. There have been rare case reports of normal pulmonary function in the presence of bilateral renal agenesis in monoamniotic discordant twins, but this has never been reported in a singleton pregnancy. The few reported cases in twins have all been fatal in the neonatal period with no reported cases of survival beyond 2 months. We describe the first case of a singleton infant with bilateral renal agenesis who had normal pulmonary function and did well on peritoneal dialysis for 4 years while awaiting a renal transplant.

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Mediastinal lymphangioma in an adult with a tracheal bronchus

Srpski arhiv za celokupno lekarstvo ◽

10.2298/sarh160712061c ◽

2017 ◽

Vol 145 (7-8) ◽

pp. 400-402

Author(s):

Mariusz Chabowski ◽

Anna Szymanska-Chabowska ◽

Malgorzata Szolkowska ◽

Dawid Janczak ◽

Dariusz Janczak

Keyword(s):

Rare Case ◽

Anterior Mediastinum ◽

Good Prognosis ◽

Benign Tumors ◽

Tracheal Bronchus ◽

Mediastinal Tumors ◽

Benign Condition ◽

Cystic Lymphangiomas ◽

Case Surgery ◽

Surgery Department

Introduction. Lymphangiomas, also known as cystic hygromas or cystic lymphangiomas, are cystic abnormalities of the lymph vessels and they are rare benign tumors. Tracheal bronchus (Bronchus suis or ?pig bronchus?) is a very rare congenital anomaly. The aim of this work is to present ? very rare case of ? lymphangioma with tracheal bronchus. Case outline. The article presents the rare case of a 35-year-old otherwise healthy man, who was admitted to our thoracic surgery department with a mediastinal tumor. On performing bronchoscopy a tracheal bronchus was found. A thoracic CT scan revealed a well-circumscribed mass in the superior and anterior mediastinum measuring 37 x 39 x 59 mm. First a Carlens mediastinoscopy, and then a right parasternal Chamberlain mediastinotomy were performed. The final pathological diagnosis of lymphangioma was made. In this case, surgery was not performed because the patient was asymptomatic and the tumor did not grow larger during follow-up. Conclusion. The lymphangioma of the mediastinum in an adult is a rare and benign condition with a good prognosis, but it should be considered in a differential diagnosis of mediastinal tumors. We recommend only a minimally invasive diagnostic approach (parasternal mediastinotomy) when the patient is asymptomatic.

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A Rare Case of Accessory Tracheal Bronchus

Journal of Medical Imaging and Case Reports ◽

10.17756/micr.2019-027 ◽

2019 ◽

Vol 03 (01) ◽

Author(s):

Gokhan Perincek ◽

Sema Avci

Keyword(s):

Rare Case ◽

Tracheal Bronchus

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Rare case of tracheal bronchus in a patient posted for minimal invasive cardiac surgery

Annals of Cardiac Anaesthesia ◽

10.4103/aca.aca_215_18 ◽

2020 ◽

Vol 23 (3) ◽

pp. 364

Author(s):

Dibyendu Khan ◽

Saikat Sengupta ◽

Sushan Mukhopadhyay ◽

Gautam Pati

Keyword(s):

Cardiac Surgery ◽

Rare Case ◽

Minimal Invasive ◽

Tracheal Bronchus ◽

Minimal Invasive Cardiac Surgery

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A rare case of tracheobronchial anomalies: 'Tracheal Bronchus'

Respiratory Case Reports ◽

10.5505/respircase.2013.47966 ◽

2013 ◽

Vol 2 (2) ◽

pp. 57-59

Author(s):

Selvi Kelekci ◽

Fatih Meteroglu ◽

Velat Sen ◽

Atalay Sahin ◽

Tahir Sevval Eren ◽

...

Keyword(s):

Rare Case ◽

Tracheal Bronchus

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A Rare Case of Late Presentation of Congenital Diaphragmatic Hernia

The Journal of Medical Sciences ◽

10.5005/jp-journals-10045-0042 ◽

2016 ◽

Vol 2 (4) ◽

pp. 65-67

Author(s):

R Nagesh ◽

Anil K Shukla ◽

Sonam Sanjay ◽

VV Seetha Pramila

Keyword(s):

Congenital Diaphragmatic Hernia ◽

Diaphragmatic Hernia ◽

Rare Case ◽

Pulmonary Hypoplasia ◽

Adult Population ◽

Clinical Problem ◽

Late Presentation ◽

The Right ◽

Major Clinical Problem ◽

Diaphragmatic Hernias

ABSTRACT Congenital diaphragmatic hernia is a well-described condition that occurs in about 1 in 5,000 live births. A majority of the patients are diagnosed either antenatal or will present in the first few hours of life with respiratory distress. Presentation in adults is extremely rare and accounts for about 5 to 25% of diaphragmatic hernias. Patients, who present with late diaphragmatic hernias, complain of a wide variety of symptoms and diagnosis can be difficult. It consists of herniation of bowel, and occasionally solid organs, into the chest. It is more common on the left side (seen in 80% of cases), as the liver provides a relative barrier on the right side. The major clinical problem is pulmonary hypoplasia, a result of the lung having failed to develop in utero as the thoracic cavity is filled with abdominal contents. These congenital diaphragmatic defects have also been described in the adult population, and the widespread use of computed tomography has led to the recognition that these hernias are not uncommon and are often asymptomatic. How to cite this article Sanjay S, Pramila VVS, Shukla AK, Nagesh R. A Rare Case of Late Presentation of Congenital Diaphragmatic Hernia. J Med Sci 2016;2(4):65-67.

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