Giant Occipital Chondroma; An Uncommon Presentation of A Rare Entity

Listeria monocytogenes is a gram positive bacillus responsible for listeriosis. This infection manifests mainly as bacteremia and / or central nervous system (CNS) infection. Involvement of other sites is rare. Pleural listeriosis is an uncommon presentation of L. monocytogenes infection and there is little data to guide the management of these patients. First-line antibiotics used empirically to treat bacterial respiratory infections are ineffective in treating these L. monocytogenes infections, which contributes to the progression of the infection and a worse prognosis. We present a case report of a patient admitted to an intensive care unit with septic shock secondary to systemic listeriosis with L. monocytogenes isolation in pleural fluid culture and blood cultures. The evolution of the hospitalization and the clinical outcome are reported.

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Successful multidisciplinary treatment of Doege-Potter syndrome: hypoglycaemia caused by paraneoplastic IGF-2 production by a metastatic haemangiopericytoma

BMJ Case Reports ◽

10.1136/bcr-2021-241724 ◽

2021 ◽

Vol 14 (4) ◽

pp. e241724

Author(s):

Jeffery Tong ◽

Jonathan Athayde ◽

Shawn MacKenzie ◽

Meghan Ho

Keyword(s):

Islet Cell ◽

Multidisciplinary Treatment ◽

Solitary Fibrous Tumour ◽

Rare Entity ◽

Tumour Burden ◽

Hepatic Tumour ◽

Solitary Fibrous Tumours ◽

Uncommon Presentation ◽

History Of ◽

Successful Approach

Hypoglycaemia due to insulin-like growth factor (IGF)-2 secretion is a paraneoplastic complication of malignancy with significant morbidity that can often go unrecognised due to its uncommon presentation. We report on a case of a 51-year-old man with metastatic haemangiopericytoma presenting with refractory hypoglycaemia, requiring continuous dextrose 10% infusion while in hospital. IGF-2 levels were significantly elevated, in keeping with a rare entity associated with solitary fibrous tumours, known as Doege-Potter syndrome. The patient was managed using uncooked cornstarch in conjunction with debulking of the hepatic tumour burden with bland IR-guided transarterial embolisation, and eventual surgical resection to treat his non-islet cell tumour hypoglycaemia (NICTH). The case highlights this rare paraneoplastic phenomenon that should be included in the differential for hypoglycaemia, especially if a history of a solitary fibrous tumour is elicited. Our case is the first to document a successful approach to treating the hypoglycaemia using preoperative transarterial bland embolisation.

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Uncommon Presentation of Isolated Jejunal Lymphoma Masquerading as Crohn’s Disease

Case Reports in Surgery ◽

10.1155/2016/5603627 ◽

2016 ◽

Vol 2016 ◽

pp. 1-3

Author(s):

Swati Sattavan ◽

Lalit Aggarwal ◽

Priyadarshi Dikshit

Keyword(s):

Crohn’S Disease ◽

Small Bowel ◽

Crohn's Disease ◽

Cell Lymphoma ◽

B Cell Lymphoma ◽

Rare Entity ◽

Gastrointestinal Lymphoma ◽

Uncommon Presentation ◽

Unusual Variant ◽

Primary Gastrointestinal Lymphoma

Primary gastrointestinal lymphoma is a rare entity, commonly involving stomach, small bowel, and colorectum. The usual location for small bowel B cell lymphoma is distal ileum due to abundant lymphoid tissue. We are reporting the case of a 53-year-old lady presumptively diagnosed as Crohn’s disease on clinical and radiological grounds but histopathologically proven to be an unusual variant of isolated primary non-Hodgkin’s lymphoma.

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Gastric Diverticulum Presenting as Hematemesis: A Case Report Detailing an Uncommon Presentation of an Already Rare Entity

Clinical Practice and Cases in Emergency Medicine ◽

10.5811/cpcem.2020.9.48603 ◽

2020 ◽

Vol 4 (4) ◽

pp. 610-612

Author(s):

Maddi Massa ◽

Karla Newbold

Keyword(s):

Case Report ◽

Gastric Resection ◽

Epigastric Pain ◽

Gastrointestinal Symptoms ◽

Rare Entity ◽

Epigastric Discomfort ◽

Treatment Regimens ◽

Uncommon Presentation ◽

Life Threatening

Introduction: Gastric diverticula (GD) are uncommon. Most are asymptomatic and diagnosed incidentally. Symptoms range from reflux and epigastric discomfort to life-threatening bleeding and perforation. We describe a case of symptomatic GD presenting as hematemesis requiring surgical treatment. Case Report: A 57-year-old female presented to the emergency department (ED) with one day of epigastric pain and hematemesis. Hemoglobin was found to be stable, but blood urea nitrogen was elevated. Imaging revealed a fundal GD. Esophagogastroduodenoscopy did not show other etiology of hematemesis. The patient underwent partial gastric resection for GD removal and did well without further symptoms on follow-up. Conclusion: Although rare, GD needs to be included on a differential diagnosis when evaluating gastrointestinal symptoms in the ED. Patients may present with an array of complaints but can potentially develop serious complications. Providers should be familiar with the diagnostic options and treatment regimens available to better care for patients presenting with GD.

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Primary Intestinal Hodgkin’s Lymphoma: An Uncommon Presentation

Journal of Laboratory Physicians ◽

10.4103/0974-2727.119866 ◽

2013 ◽

Vol 5 (02) ◽

pp. 124-126 ◽

Cited By ~ 2

Author(s):

Shruti Sharma ◽

Safia Rana ◽

Sujala Kapur ◽

Zeeba Shamim Jairajpuri

Keyword(s):

Small Intestine ◽

Hodgkin’S Lymphoma ◽

Hodgkin's Lymphoma ◽

Rare Entity ◽

Intestinal Lymphoma ◽

Common Site ◽

X Ray ◽

Uncommon Presentation ◽

Tumor Involvement ◽

Chest X Ray

ABSTRACTPrimary intestinal lymphoma is a rare lymphoproliferative neoplasm of the small intestine. The primary nature is established on the basis of lack of evidence of lymphoma on chest X-ray, computerized tomographic scan, peripheral blood or bone marrow puncture. Tumor involvement is limited to the gastrointestinal tract, the criteria for inclusion are that the symptoms related to the small intestine are predominant or the only symptoms at the time of laparotomy. Hodgkin's lymphoma (HL) primarily in the small intestine is a rare entity and an uncommon presentation of the disease. Ileum is the more common site of infliction than the jejunum because of its abundant lymphoid follicles. Here, we present a case of primary intestinal HL, in a 30-year-old male.

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A Giant Pre-Peritoneal Lipoma: A Report of an Uncommon Presentation of a Rare Entity and a Review of the Literature

Surgical Case Reports ◽

10.31487/j.scr.2021.07.13 ◽

2021 ◽

pp. 1-5

Author(s):

Ulasi Ikechukwu Bartholomew ◽

Afuwape OO ◽

Ajani MA ◽

Onyema AE ◽

...

Keyword(s):

Soft Tissue Tumor ◽

Iliac Fossa ◽

Benign Tumors ◽

Rare Entity ◽

Review Of The Literature ◽

Abdominal Ultrasonography ◽

Case Presentation ◽

Uncommon Presentation ◽

Peritoneal Space ◽

The Right

Background: A lipoma is one of the commonest benign tumors in surgical practice. Lipomas are usually found on the trunk and limbs but less commonly within the abdomen, where they occur frequently in the mesentery as well as the subserosa and submucous layer of the gastrointestinal tract. Pre-peritoneal lipomas are rare. Case Presentation: A 44-year-old woman presented with a painless and progressive right-sided abdominal swelling of 5 months duration. Examination revealed a 16cm x 14cm slightly mobile and non-tender firm-to-hard hour-glass-shaped mass extending from the right hypochondrial to right iliac and the suprapubic regions. Abdominal ultrasonography showed a 5cm x 6cm bowel thickening in the right iliac fossa suggestive of an ileocecal mass while a computerized tomography showed a 20.8cm x 6.3cm x 20.1cm hypodense mass within the peritoneal cavity, extending from the epigastric region to the pelvis, anterior to the bowel loops and more to the right. At laparotomy, a huge, well encapsulated yellowish mass in the pre-peritoneal space, weighing 1,520g was excised. Histology confirmed a lipoma. Conclusion: A preperitoneal lipoma is an uncommon soft tissue tumor and the giant ones are extremely rare. Although a rare cause of a painless abdominal swelling, pre-peritoneal lipoma should be considered as a differential diagnosis in patients presenting with an unremarkable feature suggestive of an intra-abdominal pathology.

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Schwannoma of the penis, presenting as a scrotal mass, rare entity with an uncommon presentation

Urology Annals ◽

10.4103/ua.ua_38_17 ◽

2017 ◽

Vol 9 (3) ◽

pp. 301 ◽

Cited By ~ 2

Author(s):

Ujwal Kumar ◽

NawalKishore Jha

Keyword(s):

Rare Entity ◽

Scrotal Mass ◽

Uncommon Presentation

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Bilateral congenital renal arteriovenous malformation: A rare entity with uncommon presentation

IIUM Medical Journal Malaysia ◽

10.31436/imjm.v8i1.773 ◽

2020 ◽

Vol 8 (1) ◽

Author(s):

Radhiana H ◽

Mohd Shafie A ◽

Mohd Ariff MA

Keyword(s):

Congenital Anomaly ◽

Arteriovenous Malformation ◽

Urinary System ◽

Rare Entity ◽

Rare Congenital Anomaly ◽

Uncommon Presentation ◽

Renal Arteriovenous Malformation ◽

Diagnostic Work ◽

Work Up ◽

Diagnostic Work Up

Renal arteriovenous malformation (AVM) is a rare congenital anomaly of the urinary system. We present a patient with bilateral renal AVMs who presented with back pain and microscopic hematuria. This case highlights the importance of careful diagnostic work-up in the evaluation of upper tract hematuria.

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