Concomitant bilateral mandibular cemento-ossifying fibroma and cementoblastoma: case report of an extremely rare occurrence

Abstract Background Cemento-ossifying fibroma (COF) and cementoblastoma (CB) are rare benign odontogenic tumors with a predilection for the mandible. Cemento-ossifying fibroma is a fibro-osseous lesion that originates in the tooth bearing areas of jaw and shows cementum-like tissue in a fibrotic stroma. Cementoblastoma is classically related to roots of teeth with the presence of calcified cementum-like material. To date, only a single case of concomitant unilateral COF and CB has been reported in the literature. Case presentation We present an unusual case of a 37-year-old female who presented with two discrete bilateral swellings in the right and left mandible for 10 years. The larger tumor involved the left posterior mandible with extension anteriorly to the left and right anterior mandibles, and the smaller tumor was present in right posterior mandible. Radiology revealed two distinct lesions involving both sides of mandible. Histopathological examination showed characteristic features of cemento-ossifying fibroma in sections of the larger tumor and cementoblastoma in sections of smaller tumor. Conclusion This case shows the very unique bilateral co-existence of COF and CB, the second case reported in literature to date.

Download Full-text

The largest reported intrathoracic lipoma: a case report and current perspectives review

Journal of Cardiothoracic Surgery ◽

10.1186/s13019-019-1030-8 ◽

2019 ◽

Vol 14 (1) ◽

Author(s):

Mohammed Aldahmashi ◽

Abdalmotaleb Elmadawy ◽

Mahmoud Mahdy ◽

Mohamed Alaa

Keyword(s):

Single Case ◽

Tumor Resection ◽

Pathological Examination ◽

Complete Excision ◽

Case Presentation ◽

Medical Checkup ◽

Excellent Outcome ◽

The Right ◽

Intrathoracic Mass

Abstract Background The huge size intrathoracic lipomas are very rare. Few cases have been reported worldwide. To our knowledge, this presented case is one of the few cases reported. Here we report a single case as very huge intrathoracic lipoma compressing the right lung and displacing the diaphragm and liver downward. It has been managed by right posterolateral thoracotomy and complete excision, with excellent outcome. Case presentation A 32-year-old male presented with a symptomatic right intrathoracic mass, which was confirmed to be a lipomatous tumor using computed tomography. A penduculated tumor originating from the mediastinal pleura was resected through the conventional right posterior thoracotomy. Pathological examination indicated a diagnosis of fibrolipoma. Conclusion The tumor was symptomatic and relatively huge when detected during a medical checkup. This enabled the successful tumor resection via conventional thoracotomy approach. Although intrathoracic lipomas are histologically benign, careful observation and follow-up are crucial due to the possibility of recurrence.

Download Full-text

Right hemisphere speech perception revealed by amobarbital injection and electrical interference

Neurology ◽

10.1212/wnl.51.2.458 ◽

1998 ◽

Vol 51 (2) ◽

pp. 458-464 ◽

Cited By ~ 26

Author(s):

D. Boatman ◽

J. Hart ◽

R. P. Lesser ◽

N. Honeycutt ◽

N. B. Anderson ◽

...

Keyword(s):

Speech Perception ◽

Left Hemisphere ◽

Temporal Lobe ◽

Right Hemisphere ◽

Adult Brain ◽

Left Posterior ◽

Left And Right ◽

Sodium Amobarbital ◽

The Right ◽

Electrical Interference

Objective: To investigate the right hemispheric speech perception capabilities of an adult right-handed patient with seizures.Methods: Consecutive, unilateral, intracarotid sodium amobarbital injections and left hemispheric electrical interference mapping were used to determine lateralization and localization of speech perception, measured as syllable discrimination.Results: Syllable discrimination remained intact after left and right intracarotid sodium amobarbital injections. Language otherwise strongly lateralized to the left hemisphere. Despite evidence of bilateral speech perception capabilities, electrical interference testing in the left posterior temporal lobe impaired syllable discrimination.Conclusions: The results suggest a functionally symmetric, parallel system in the adult brain with preferential use of left hemispheric pathways for speech perception.

Download Full-text

Primary epithelioid rhabdomyosarcoma of the stomach: a case report and review of literature

Diagnostic Pathology ◽

10.1186/s13000-019-0917-y ◽

2019 ◽

Vol 14 (1) ◽

Author(s):

Yangkun Wang ◽

Pei Guo ◽

Zhishang Zhang ◽

Runde Jiang ◽

Zuguo Li

Keyword(s):

Tumor Cells ◽

Unusual Case ◽

Histopathological Examination ◽

Gastroesophageal Junction ◽

Rare Tumor ◽

Review Of Literature ◽

Ki 67 ◽

Case Presentation ◽

Cytoplasmic Content ◽

Mitotic Figures

Abstract Background Epithelioid rhabdomyosarcoma is a rare tumor that generally occurs in the bladder, the parotid gland, or the skin of the neck. We describe an unusual case of primary epithelioid rhabdomyosarcoma of the stomach and review the literature. Case presentation A 64-year-old woman presented with a lesion at the gastroesophageal junction. Histopathological examination showed irregularly sized round cells with low cytoplasmic content and eccentric nuclei. Mitotic figures were present. Fibrovascular septa and areas of necrosis were observed between tumor cells. Tumor cells were strongly positive for MyoD1, desmin, and myogenin, and weakly positive for actin, CD56, and PGP9.5. The ki-67 index was ≥90%. Conclusions Primary epithelioid rhabdomyosarcoma of the stomach is extremely rare. Better awareness of this entity is necessary for early diagnosis and treatment.

Download Full-text

Desmoplastic Fibroma and Cemento Ossifying Fibroma of The Anterior Maxilla: A Rare Case Report

Dentika Dental Journal ◽

10.32734/dentika.v24i1.5613 ◽

2021 ◽

Vol 24 (1) ◽

pp. 21-27

Author(s):

Victor Pakpahan ◽

Eky Nasuri ◽

Vera Julia

Keyword(s):

Rare Case ◽

Histopathological Examination ◽

Neck Region ◽

The Body ◽

Ossifying Fibroma ◽

Desmoplastic Fibroma ◽

Anterior Maxilla ◽

Main Complaint ◽

Rare Case Report ◽

The Right

Tumors located in the maxillofacial part of the body were classified by WHO in 2017 and among these are intraosseous form of fibromatosis known as Desmoplastic and Cemento-ossifying fibromas. These tumors usually occur in the head and neck region, especially in the mandible and are relatively rare in the maxilla. Meanwhile, this study aims to discribe a rare case of the cemento ossifying fibroma that had been previously diagnosed as desmoplastic fibroma with a mass tumor in the anterior of the maxilla. A 22 years old female reported to the Cipto Mangkusumo Hospital with the main complaint of a lump in the right side of the upper jaw which appeared 2 years prior to the operation. In April 2017, the patient had a biopsy in Tarakan Hospital and the result was a desmoplastic fibroma. Due to the lump enlargement, the patient was admitted to RSCM in July 2019 and had biopsy incision with a diagnosis of cemento ossifying fibroma which was confirmed by the histopathological examination and histology report. The resection of the right part of maxilla was conducted alongside with reconstruction using the free fibular flap. Moreover, cemento ossifying fibroma and desmoplastic fibroma shared similar features, namely, clinical, histological and radiological features which are important in establishing the diagnosis and treatment of patient. Hence, extensive enucleation or resection is required due to the progressive nature of the tumor to prevent the potential for further recurrences.

Download Full-text

Primary leiomyoma of the ureter: a case report

Journal of Medical Case Reports ◽

10.1186/s13256-021-02960-w ◽

2021 ◽

Vol 15 (1) ◽

Author(s):

Shingo Morinaga ◽

Shigeyuki Aoki ◽

Motoi Tobiume ◽

Genya Nishikawa ◽

Hiroyuki Muramatsu ◽

...

Keyword(s):

Malignant Tumors ◽

Histopathological Examination ◽

Urine Cytology ◽

Benign Tumors ◽

Case Presentation ◽

Old Japanese ◽

Retrograde Pyelogram ◽

History Of ◽

The Right ◽

Enhanced Computed Tomography

Abstract Background Only 14 cases of leiomyoma with ureteral origin have been reported previously. Such primary leiomyomas often present as hydronephrosis, making the diagnosis difficult. Radical nephroureterectomy is often performed because of the possible diagnosis of a malignant tumor. We report the 15th case of primary leiomyoma with a ureteral origin. Case presentation A 51-year-old Japanese man presented with a chief complaint of asymptomatic gross hematuria with a history of hypertension. Enhanced computed tomography showed a tumor at the upper part of the right ureter that appeared to be the cause of hydronephrosis and contracted kidney; no retroperitoneal lymphadenopathy and distal metastasis were observed. A well-defined 20-mm (diameter) defect was identified at the upper of the right ureter on retrograde pyelogram with no bladder cancer on cystoscopy. Urine cytology and right divided renal urine cytology findings were negative. Laparoscopic nephroureterectomy was performed, and the extracted tumor measured 20 × 13 mm. Histopathological examination revealed primary leiomyoma with no recurrence 16 months after the operation. Conclusions Preoperative examination with the latest available ureteroscopic technology can help preserve renal function in the case of benign tumors by enabling preoperative ureteroscopic biopsy or intraoperative rapid resection. Moreover, nephroureterectomy is recommended in the case of preoperative suspicion of ureteral malignant tumors.

Download Full-text

Case report: rare presentation of primary angiomyolipoma in the middle ear

BMC Surgery ◽

10.1186/s12893-020-00956-9 ◽

2020 ◽

Vol 20 (1) ◽

Author(s):

Fei Wang ◽

Hao Wang

Keyword(s):

Magnetic Resonance Imaging ◽

Computed Tomography ◽

Middle Ear ◽

Unusual Case ◽

Histopathological Examination ◽

Resonance Imaging ◽

Rare Presentation ◽

Case Presentation ◽

Common Chronic Disease ◽

Middle Ear Cholesteatoma

Abstract Background Angiomyolipoma (AML) is a common, chronic disease usually localized in kidney and liver organs; but occurring frequently outside the kidney or liver. Case presentation We describe an unusual case of a 62-year-old female patient with AML in the middle ear. She presented with left earache, tinnitus and hearing loss. Preoperative computed tomography and magnetic resonance imaging seemed to reveal a middle ear cholesteatoma. The patient underwent surgical resection of this lesion, and the AML was finally confirmed by histopathological examination. The patient was discharged on the 8th postoperative day and did not seek further treatment. Conclusions Extraperitoneal AML is rare and accurately identified by histopathology. The recommended management is surgery for AML in the middle ear.

Download Full-text

Benign mesenteric lipomatous tumor in a child: a case report and literature review

Surgical Case Reports ◽

10.1186/s40792-020-01020-7 ◽

2020 ◽

Vol 6 (1) ◽

Author(s):

Naoki Hashizume ◽

Takato Aiko ◽

Suguru Fukahori ◽

Shinji Ishii ◽

Nobuyuki Saikusa ◽

...

Keyword(s):

Histopathological Examination ◽

Abdominal Mass ◽

Soft Tissue Tumors ◽

Resonance Imaging ◽

Case Presentation ◽

Lipomatous Tumor ◽

Longitudinal Length ◽

The Right ◽

Left Abdomen ◽

Lipomatous Tumors

Abstract Background Lipomatous tumors are the most common type of soft-tissue tumors. Benign lipomatous tumors are lipomas and lipoblastoma. We herein report a case of benign mesenteric lipomatous tumor and the largest collection of known benign mesenteric lipomatous tumors in children in the literature. Case presentation A 3-year-old girl presented with repeated dull abdominal pain and left abdominal mass swelling. On a physical examination, the child had a soft, moderately distended left abdomen that was not tender when palpated. Computed tomography and magnetic resonance imaging demonstrated a large fatty mass within the mesentery, measuring approximately 8 × 6 cm. The mass extended from the right upper quadrant to the lower pole of the kidneys. Laparotomy with resection of the mesenteric tumor was performed under general anesthesia. A well-capsuled tumor was a soft, yellow mass and found loosely attached to the mesenterium of the ileum. A histopathological examination demonstrated the lobular proliferation of mature adipocytes. Atypical lipoblasts were not seen. These features are compatible with benign lipomatous tumor, such as lipoma or lipoblastoma with maturation. Conclusion In conclusion, benign mesenteric lipomatous tumors tend to be large in size over 10 cm in longitudinal length. However, resection is well tolerated in the vast majority of cases with benign post-operative courses.

Download Full-text

Delayed bronchial perforation after bulla cauterization with soft coagulation system

Surgical Case Reports ◽

10.1186/s40792-021-01327-z ◽

2021 ◽

Vol 7 (1) ◽

Author(s):

Sakiko Kumata ◽

Katsunari Matsuoka ◽

Shinjiro Nagai ◽

Mitsuhiro Ueda ◽

Yoshinori Okada ◽

...

Keyword(s):

Unusual Case ◽

Muscle Flap ◽

Coagulation System ◽

Bronchial Wall ◽

Case Presentation ◽

Bronchial Anastomosis ◽

Soft Coagulation ◽

Delayed Perforation ◽

Intercostal Muscle Flap ◽

The Right

Abstract Background Soft coagulation is widely used for hemostasis because of its significant advantage in inducing tissue coagulation and denaturation without carbonization. However, a few cases of airway damage have been reported at the site, where soft coagulation was directly applied. Case presentation We encountered an unusual case of delayed perforation of the intermediate bronchial trunk observed on 24 days after cauterization of the right S6 bulla adjacent to the bronchus. Chest computed tomography revealed a large fistula between the intermediate bronchial trunk and the cauterized bulla in the right S6. Bronchoscopy showed a large fistula at the membranous portion of the intermediate bronchial trunk. We presumed that the bronchial perforation resulted from thermal damage to the intermediate bronchial trunk during bulla cauterization and the bronchial perforation induced infection in the bulla. Resection of the infectious bulla and the intermediate bronchial trunk, followed by end-to-end bronchial anastomosis and a pedicled intercostal muscle flap coverage, was performed. Conclusions The severe airway damage resulting in perforation developed even without direct contact between the electrode tip and the bronchial wall, provoking the need for special attention to the duration of cauterization and location, where it is used.

Download Full-text

Congenital orbital teratoma: A case report

Journal of Neonatal Surgery ◽

10.47338/jns.v9.523 ◽

2020 ◽

Vol 9 ◽

pp. 9

Author(s):

Ahmed Raza ◽

Asma Mushtaq ◽

Seema Qayyum ◽

Fiza Azhar ◽

Ahmad Imran ◽

...

Keyword(s):

Histopathological Examination ◽

Cystic Teratoma ◽

Surgical Excision ◽

Unusual Site ◽

Case Presentation ◽

Neonatal Life ◽

Complete Surgical Excision ◽

Sacrococcygeal Region ◽

The Right ◽

Unilateral Proptosis

Background: Teratoma originates from all three germinal layers and commonly found at the sacrococcygeal region. The orbit is an unusual site of occurrence, but they grow rapidly and cause massive proptosis. Case Presentation: A 9-day-old female neonate presented with marked unilateral proptosis of the right eye. Imaging workup gave a suspicion of a complex mass with internal hemorrhage or a teratoma. Modified exenteration was performed. Histopathological examination revealed mature cystic teratoma. Conclusion: Orbital teratoma presents with marked disfiguring proptosis in neonatal life. Prompt complete surgical excision is curative in the case of mature lesions.

Download Full-text

Calcified brain metastatic adenocarcinoma: A case report and review of the literature

The Neuroradiology Journal ◽

10.1177/1971400918805184 ◽

2018 ◽

Vol 32 (1) ◽

pp. 57-61

Author(s):

Eshagh Bahrami ◽

Morteza Taheri ◽

Mohsen Benam

Keyword(s):

Brain Metastasis ◽

Histopathological Examination ◽

Occipital Lobe ◽

Clonic Seizure ◽

Brain Parenchyma ◽

Metastatic Adenocarcinoma ◽

Case Presentation ◽

Rim Enhancement ◽

Autopsy Specimens ◽

The Right

Introduction Calcification in brain metastasis occurs rarely so it is reported in approximately 1% of surgical and 6.6% of autopsy specimens. Here we report a new case of brain metastasis with calcification. Case presentation A 44-year-old woman presented with a generalized tonic–clonic seizure with no neurological deficit on physical examination. Brain imaging demonstrated a hyperdense lesion on computed tomography scan and hyposignal and rim enhancement on T1, T2 and T1 with gadolinium injection sequence images in the right parieto-occipital lobe. Intraoperatively, there was a well-defined solid homogenous calcified mass within brain parenchyma. The lesion that resembled a meningioma was totally resected. The histopathological examination revealed metastatic adenocarcinoma. Conclusion Metastatic brain lesions should be in the differential diagnosis of a solitary calcified brain mass, although it occurs rarely. It is important to differentiate it radiologically from intralesional haemorrhage.

Download Full-text