scholarly journals Bilateral Pulmonary Langerhans's Cell Histiocytosis is Surgical Challenge in Children: A Case Report

2019 ◽  
Vol 07 (01) ◽  
pp. e8-e11
Author(s):  
Tutku Soyer ◽  
Gül Özyüksel ◽  
Özlem Boybeyi Türer ◽  
Kübra Çakmakkaya ◽  
Sinan Yavuz ◽  
...  
Keyword(s):  
Case Report ◽  
Respiratory Distress ◽  
Treatment Options ◽  
Surgical Excision ◽  
Neck Mass ◽  
Treatment Alternative ◽  
Lethal Outcome ◽  
Talc Pleurodesis ◽  
Severe Respiratory Distress ◽  
Surgical Options

Background Pulmonary Langerhans's cell histiocytosis (PLCH) is a rare cause of interstitial lung disease in children and more than half of the cases are bilateral. Persistent respiratory distress due to spontaneous pneumothorax (SP) in bilateral PLCH may refractory to conservative treatment and posed a great challenge to surgical modalities. A 3-year-old boy with SP due to bilateral PLCH is presented to discuss the surgical options of recurrent and refractory PLCH cases in children. Case Report The patient was admitted to the emergency department with severe respiratory distress and SP. After chest tube insertion, biopsy from neck mass revealed Langerhans's cell histiocytosis. Chemotherapy including vinblastine and prednisone was initiated. Due to persistent respiratory difficulty and air leaks, talc pleurodesis and thoracoscopic bullae excision with pleural decortication were performed. Two months after the admission, due to nosocomial infection and severe respiratory distress, extracorporeal membranous oxygenation (ECMO) support was initiated. The patient was died of ECMO complications on 24th day of ECMO. Conclusion Despite the use of chemotherapy and surgical excision of cystic lesions, bilateral PLCH in children may have lethal outcome. Other treatment options including respiratory support with ECMO and lung transplantation should be considered as last resort of treatment alternative in persistent cases.

Multiple symmetrical lipomatosis: case report and literature review

2012 ◽  
Vol 126 (7) ◽  
pp. 756-758 ◽  
Author(s):  
K J Sia ◽  
I P Tang ◽  
T Y Tan
Keyword(s):  
Computed Tomography ◽  
Case Report ◽  
Literature Review ◽  
Clinical Examination ◽  
Surgical Excision ◽  
Neck Mass ◽  
Disease Extent ◽  
Treatment Methods ◽  
Surgical Options ◽  
Symmetrical Lipomatosis

AbstractObjective:To discuss the pathophysiology and various treatment methods of multiple symmetrical lipomatosis.Case report:We report a case of multiple symmetrical lipomatosis in a middle-aged man. He presented to us with an extensive, disfiguring neck mass. Clinical examination and computed tomography suggested a lipomatous mass without compression of vital neck structures. The proximity of the lipomatous mass to the carotid sheaths attracted our interest. We performed surgical excision in this case, because of the deep infiltrative behaviour of the lipoma. The benefits and drawbacks of liposuction and surgical excision of extensive neck lipomatosis are discussed.Conclusion:Surgical excision and liposuction are complementary treatments in the management of multiple symmetrical lipomatosis. Patients should be aware of the limitations of both surgical options, and the risk of lipoma recurrence, before surgery. The decision on the mode of surgery relies upon the disease extent, the patient's expectations and the surgeon's experience.

scholarly journals Extensive parapharyngeal and skull base neuroglial ectopia; a challenge for differential diagnosis and treatment: case report

2010 ◽  
Vol 128 (5) ◽  
pp. 302-305 ◽  
Author(s):  
Giulianno Molina de Melo ◽  
Gabrielle do Nascimento Holanda Gonçalves ◽  
Ricardo Antenor de Souza e Souza ◽  
Danilo Anunciatto Sguillar
Keyword(s):  
Differential Diagnosis ◽  
Case Report ◽  
Skull Base ◽  
Infratemporal Fossa ◽  
Newborn Infants ◽  
Surgical Excision ◽  
Neck Mass ◽  
Oral Feeding ◽  
Feeding Difficulties ◽  
Complete Surgical Excision

CONTEXT: Neuroglial ectopia has been defined as a mass composed of differentiated neuroectodermal tissue isolated from the spinal canal or cranial cavity and remains rare. This lesion has to be considered in the differential diagnosis among newborn infants with classical symptoms of respiratory distress, neck mass and feeding difficulties. We present a rare case of extensive parapharyngeal and skull base neuroglial ectopia in 6-month-old girl who presented respiratory and feeding obstruction at birth. CASE REPORT: A six-month-old girl who presented upper respiratory and feeding obstruction at birth and was using tracheostomy and gastrostomy tubes was referred to our institution. Complete surgical excision of the mass consisted of a transcervical-transparotid approach with extension to the infratemporal fossa by means of a lateral transzygomatic incision, allowing preservation of all vital neurovascular structures. The anatomopathological examination showed a solid mass with nests of neural tissue, with some neurons embedded in poorly encapsulated fibrovascular stroma, without mitotic areas, and with presence of functioning choroid plexus in the immunohistochemistry assay. Neurovascular function was preserved, thus allowing postoperative decannulation and oral feeding. Despite the large size of the mass, the child has completed one year and six months of follow-up without complications or recurrence. Neuroglial ectopia needs to be considered in diagnosing airway obstruction among newborns. Surgical treatment is the best choice and should be performed on clinically stable patients. An algorithm to guide the differential diagnosis and improve the treatment was proposed.

scholarly journals Nonfunctional parathyroid cyst: case report

2009 ◽  
Vol 127 (6) ◽  
pp. 382-384 ◽  
Author(s):  
Carlos Eduardo Molinari Nardi ◽  
Ricardo Adriano Nasser Barbosa da Silva ◽  
Cynthia Maria Massarico Serafim ◽  
Rogério Aparecido Dedivitis
Keyword(s):  
Case Report ◽  
Surgical Excision ◽  
Neck Mass ◽  
Thyroid Lobe ◽  
Parathyroid Cyst ◽  
Neck Masses ◽  
Thyroid Lobectomy ◽  
Ionic Calcium ◽  
Parathyroid Cysts ◽  
Left Thyroid Lobe

CONTEXT: Parathyroid cysts are rare clinical and pathological entities, with less than 300 cases reported. The inferior parathyroid glands are most commonly involved, with left-side predominance. Parathyroid cysts may be functional or nonfunctional, depending on their association with hypercalcemia. CASE REPORT: A 25-year-old man presented a palpable asymptomatic left-side neck mass. Ultrasound revealed a cystic structure contiguous with the left thyroid lobe. Serum ionic calcium was normal. The patient underwent left thyroid lobectomy plus isthmectomy with excision of the cyst. The histological findings revealed a parathyroid cyst. Parathyroid cysts typically present as asymptomatic neck masses, and surgical excision appears to be the treatment of choice.

scholarly journals Acute Respiratory Distress due to Thymoma in a Patient Treated with TK Inhibitor: A Case Report and Review of the Current Treatment Options

2011 ◽  
Vol 4 (1) ◽  
pp. 155-161
Author(s):  
P. Zarogoulidis ◽  
D. Matthaios ◽  
A. Iordanidis ◽  
V. Zervas ◽  
A. Mitrakas ◽  
...  
Keyword(s):  
Case Report ◽  
Respiratory Distress ◽  
Treatment Options ◽  
Current Treatment

The challenging airway: Tracheal agenesis in the newborn

2021 ◽  
pp. 1-3
Author(s):  
A.P. Akhter ◽  
S.M. Donn
Keyword(s):  
Respiratory Distress ◽  
Congenital Heart Defect ◽  
Tracheoesophageal Fistula ◽  
Congenital Heart ◽  
Congenital Abnormalities ◽  
Delivery Room ◽  
Tracheal Agenesis ◽  
Severe Respiratory Distress ◽  
Heart Defect ◽  
Surgical Options

A preterm female presented with severe respiratory distress in the delivery room and was found to have tracheal agenesis with a tracheoesophageal fistula and a congenital heart defect. Tracheal agenesis is uncommon and is often associated with other congenital abnormalities. Although there are surgical options for repair, mortality remains high.

scholarly journals Spontaneous massive hemothorax following snakebite envenomation: a case report

2021 ◽  
Author(s):  
Yosief Yemane ◽  
Mulugeta Russom
Keyword(s):  
Case Report ◽  
Respiratory Distress ◽  
Unusual Case ◽  
Severe Respiratory Distress ◽  
Close Observation ◽  
Massive Hemothorax

This unusual case of massive hemothorax developed following snakebite envenomation resulted in massive drop in hemoglobin, from 13.2 to 3.1g/dL, in three-days, and severe respiratory distress that required a number of thoracocentesis. He was stable until day-two of admission, then fully-deteriorated on day-three which reflects the need for close observation.

scholarly journals CASE REPORT ON EPIDERMOLYSIS BULLOSA- A RARE DISORDERS

2016 ◽  
Vol 3 (3) ◽  
pp. 298-300
Author(s):  
Dileepreddy Gottimuukula ◽  
Rakesh Chakinala ◽  
Surender Kagithapu ◽  
Yogi Morishetty ◽  
Goverdhan Puchchakayala
Keyword(s):  
Respiratory Distress ◽  
Epidermolysis Bullosa ◽  
Wound Care ◽  
Treatment Options ◽  
Specific Treatment ◽  
Skin Lesions ◽  
Rare Disorders ◽  
Severe Respiratory Distress ◽  
Male Neonate ◽  
Rare Group

Epidermolysis bullosa is a rare group of skin disorders which is characterized by extreme fragility of skin and mucous memberane, which leads to formation of blisters and skin lesions. It affects 1 out of every 50,000 live births. There is no specific treatment, daily wound care and pain management are the only available treatment options. Here we report a case of male neonate with epidermolysis bullosa and respiratory distress. The neonate was died due to severe respiratory distress.

scholarly journals Transfemoral embolization of a large symptomatic renal angiomyolipoma in a horseshoe kidney: a case report and literature review

2020 ◽  
Vol 1 (2) ◽  
pp. 139-143
Author(s):  
Benjamin D Sarkodie ◽  
Dorothea A Anim ◽  
Bashiru B Jimah
Keyword(s):  
Case Report ◽  
Tumour Size ◽  
Treatment Options ◽  
Horseshoe Kidney ◽  
Arterial Embolization ◽  
Surgical Excision ◽  
Renal Angiomyolipoma ◽  
Review Of The Literature ◽  
First Line ◽  
Invasive Techniques

Renal angiomyolipomas (AML) are the commonest benign renal neoplasms. They are composed of blood vessels, adipose tissue, and smooth muscle in varying amounts. It is quite rare to find AML in a horseshoe kidney, although there is at least one such reported case discovered in pregnancy and managed by resection. Spontaneous hemorrhage which could be fatal is the most feared sequelae of AML. The first-line of management for AMLs was previously surgical excision. However, advances in minimally invasive techniques that have a lower risk of complications have broadened treatment options for reducing tumour size and preventing hemorrhage. One of such effective techniques is selective arterial embolization (SAE) of renal AMLs > 4cm. Patients not requiring any immediate intervention maybe followed up with active surveillance. In this case report, we present a case of AML in a horseshoe kidney that was successfully treated with transfemoral embolization as well as a review of the literature.

scholarly journals Respiratory obstruction due to tonsillar lymphoglandular polyp in a brachycephalic dog: a case report

2021 ◽  
Vol 17 (1) ◽  
Author(s):  
Leah Gabriel ◽  
Yazdan Aryazand ◽  
Nicole Buote
Keyword(s):  
Respiratory Distress ◽  
Co2 Laser ◽  
Emergency Service ◽  
Clinical Signs ◽  
Surgical Excision ◽  
Respiratory Obstruction ◽  
Severe Respiratory Distress ◽  
Working Space ◽  
Carbon Dioxide Co2 ◽  
The Masses

Abstract Background Respiratory distress is one of the most common afflictions of brachycephalic dogs. Dogs in respiratory distress usually present to the emergency service with a constellation of clinical signs including but not limited to: stertorous breathing, dyspnea, gagging, cyanotic mucus membranes, hyperthermia, and commonly a history of gastrointestinal signs. While Brachycephalic Obstructive Airway Syndrome is the most common cause of respiratory distress in dogs with brachycephalic conformation, any condition eliciting an inflammatory response in the oropharynx, can result in obstruction. There is no previous report of respiratory obstruction leading to emergency tonsillectomy caused by tonsillar polyps. Case presentation A 9-month-old male intact English bulldog presented to the emergency service in severe respiratory distress. Due to continued severe dyspnea and cyanosis the patient was induced with propofol (Propofol, Hospira) 4 mg/kg intravenously titrated to effect and tracheal intubation performed. Intubation was noted to be difficult due the presence of two, large, inflamed masses in the oropharynx region. The remainder of his physical exam was unremarkable. Minimum database blood work and chest radiographs revealed only minor abnormalities. The patient was placed under anesthesia and the masses were transected sharply using a carbon dioxide (CO2) laser (Aesculight, Bothell, WA, USA). Anesthesia and recovery were uneventful, and the patient was discharged the following day. Histopathology results of the masses revealed them to be benign lymphoglandular polyps. Conclusions This is the first report of bilateral tonsillar polyps causing life-threatening respiratory obstruction in a dog. Both masses were excised safely and completely with the CO2 laser. Difficulties inherent to oropharyngeal surgery include the hemorrhage, small working space, tissue swelling and difficult visualization. Surgical excision of these polyps alleviated all emergent and chronic clinical signs, and the patient’s remains healthy 12-months post-treatment.

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