Necrotizing Anterior Scleritis in a Woman with Terrien’s Marginal Degeneration: A Case Report

Purpose: The aim of the study was to report the first case of a patient with Terrien’s Marginal Degeneration (TMD) who developed necrotizing anterior scleritis without systemic disease association, requiring systemic immunosuppressive treatment. Case Report: A 32-year-old female consulted for bilateral ocular burning and hyperemia. Initially, she was diagnosed with conjunctivitis and treated with topical antibiotics and corticosteroids, with mild transitory improvement but the progression of the disease. Years later, she attended the ocular immunology consultation for a second opinion where TMD with ocular inflammatory component OU was diagnosed. Seven months later, she presented with severe pain, decreased visual acuity, and photophobia in OS. At the slit-lamp examination, necrotizing anterior scleritis with a high risk of perforation in OS was observed. The patient was referred to the rheumatologist and started treatment with systemic corticosteroids and cyclophosphamide, exhibiting a clinical improvement. The patient did not meet the criteria for any systemic illness associated with scleritis, such as autoimmune diseases or vasculitis. Thus, scleritis was related to the adjacent inflammatory process associated with TMD, as an atypical presentation of this disease. Conclusion: Although an inflammatory type of TMD has been proposed, it is essential to follow up closely these patients and consider necrotizing anterior scleritis, a severe ocular disease that requires prompt immunosuppressive management, as a possible atypical associated presentation of this disease.

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Acute Hydrops with Micro-Cornea – an Extremely Rare Condition: A Case Report

Ophthalmology Point of Care ◽

10.5301/oapoc.0000003 ◽

2017 ◽

Vol 1 (1) ◽

pp. oapoc.0000003

Author(s):

Tuhin Chowdhury ◽

Aditya Pradhan

Keyword(s):

Optical Coherence Tomography ◽

Case Report ◽

General Anaesthesia ◽

Systemic Disease ◽

Anterior Segment ◽

Rare Condition ◽

First Case ◽

Intracameral Injection ◽

Lost To Follow Up

Purpose To report the first case of a one-eyed child with micro-cornea, coloboma of iris and acute hydrops without any other disorder of the cornea or systemic disease. Methods Intracameral injection of perfluoro propane (C3F8) gas was performed under general anaesthesia. Results Resolution of the hydrops was observed at 1st week of follow-up, which was confirmed by anterior segment optical coherence tomography. Patient was subsequently lost to follow-up. Conclusions Intracameral injection of perfluoro propane gas is an effective way to quickly resolve acute hydrops. In this specific case, the patient presented with micro-cornea and no other corneal abnormalities.

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First reported case of penile prosthesis infection from brucellosis: case report

African Journal of Urology ◽

10.1186/s12301-020-00090-1 ◽

2020 ◽

Vol 26 (1) ◽

Author(s):

Nabil Nabil Moohialdin ◽

Ahmad Shamsodini ◽

Steven K. Wilson ◽

Osama Abdeljaleel ◽

Ibrahim Alnadhari ◽

...

Keyword(s):

Case Report ◽

Broad Spectrum ◽

Surgical Intervention ◽

Penile Prosthesis ◽

Raw Milk ◽

Prosthesis Infection ◽

Case Presentation ◽

First Case ◽

Milk Ingestion

Abstract Background Infection after the penile prosthesis can be devastating to both the patient and surgeon with various complications and consequences. After introduction of antibiotic-coated implants, the rate of infection has dramatically decreased, but still we see uncommon organisms causing infection. We present a first case report of penile prosthesis infection by brucellosis due to raw milk ingestion. To our knowledge, this is the first reported case of brucellosis penile prosthesis infection. Case presentation We present a first case report of penile prosthesis infection by brucellosis due to raw milk ingestion. A 75-year-old, diabetic male patient presented with penile prosthesis infection 5 months post-penile exchange surgery due to mechanical malfunctioning of 2-piece penile prosthesis which was inserted 11 years ago. The initial treatment with broad spectrum antibiotics did not subside the infection. After diagnosis of brucellosis, the antibiotic was changed to anti-brucellosis (Rifampicin + Tetracycline). The patient improved dramatically and was discharged home with smooth follow-up course. Conclusion Brucellosis can cause infection of penile prosthesis and can be treated with anti-brucellosis antibiotics without necessitating surgical intervention and removal of prosthesis.

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CONGENITAL MICROGASTRIA, A CASE REPORT WITH A 26-YEAR FOLLOW-UP

PEDIATRICS ◽

10.1542/peds.51.6.1037 ◽

1973 ◽

Vol 51 (6) ◽

pp. 1037-1041

Author(s):

Eugene Blank ◽

Alvin Chisolm

Keyword(s):

Case Report ◽

English Language ◽

Normal Adult ◽

Healthy Children ◽

Adult Size ◽

Persistent Vomiting ◽

First Case ◽

English Language Journal ◽

Roentgenographic Examination

A 27-year-old woman had congenital microgastria, which was apparent in roentgenographic examination when she was 1 year of age. Despite inability to eat anything but pureed foods for the first 13 years and despite persistent vomiting during that time, she has reached normal adult size and has three healthy children. This report represents two firsts: the first case of congenital microgastria in an English language journal of pediatrics and the first with a long follow-up.

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Teratoma of larynx: case report

International Journal of Otorhinolaryngology and Head and Neck Surgery ◽

10.18203/issn.2454-5929.ijohns20213909 ◽

2021 ◽

Vol 7 (10) ◽

pp. 1700

Author(s):

Rakesh Srivastava ◽

Vini Tandon

Keyword(s):

Carbon Dioxide ◽

Case Report ◽

Germ Cells ◽

Carbon Dioxide Laser ◽

Rare Case ◽

Histopathological Examination ◽

Flexible Laryngoscopy ◽

First Case ◽

Congenital Teratoma

<p class="abstract">Teratomas are embryonal neoplasm arises from totipotent germ cells. They are having tissues from all the three blastodermic layers. There are various locations of congenital teratoma. Naso-oropharyngeal site teratoma are either sessile or pedunculated. We describe a rare case of laryngeal teratoma in a five years old patient presented with change in voice and breathing difficulty. On flexible laryngoscopy, it appeared like supraglottic cyst but on CT scan it was confirmed as teratoma. Pre-operative tracheostomy and transoral carbon dioxide laser assisted excision done. Histopathological examination showed osteoid trabeculae, chondroid tissue with loose myxoid islands and adipose tissue. No recurrence of tumor on 18 months follow-up. This is the first case report of pediatric larynx teratoma reported in present century.</p>

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Inflammatory Myofibroblastic Tumor of the Epiglottis Excised with a Carbon Dioxide Laser: Case Report and Literature Review

Ear Nose & Throat Journal ◽

10.1177/014556131809700806 ◽

2018 ◽

Vol 97 (8) ◽

pp. E31-E33 ◽

Cited By ~ 1

Author(s):

Blake Raggio ◽

Neil Chheda

Keyword(s):

Carbon Dioxide ◽

Case Report ◽

Adjuvant Therapy ◽

Literature Review ◽

Carbon Dioxide Laser ◽

Inflammatory Myofibroblastic Tumor ◽

Benign Neoplasm ◽

First Case ◽

Laser Excision

Inflammatory myofibroblastic tumor (IMT) is a benign neoplasm of intermediate biologic potential. It rarely occurs in the larynx, and it has not been previously reported in the epiglottis. We treated a 66-year-old woman who presented with progressive dysphonia and a mass on her suprahyoid epiglottis. The tumor was completely excised with a CO2 laser; no adjuvant therapy was administered. Histopathology revealed that the mass was an IMT. No evidence of recurrence was noted after 6 months of follow-up. We present what we believe is the first case of an epiglottic IMT to be reported in the literature, and we propose CO2 laser excision without adjuvant therapy as an acceptable treatment.

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Is choriocapillaris the early target in acute maculopathy secondary to hand, foot, and mouth disease? A case report

European Journal of Ophthalmology ◽

10.1177/1120672120982522 ◽

2020 ◽

pp. 112067212098252

Author(s):

Pietro Maria Talli ◽

Edlira Bendo ◽

Emilio Pedrotti ◽

Alberto Pazzaglia

Keyword(s):

Case Report ◽

Foot And Mouth Disease ◽

Mouth Disease ◽

Ocular Involvement ◽

Primary Target ◽

Retrospective Case ◽

First Case ◽

Foot And Mouth ◽

Acute Maculopathy

Purpose: To report the case of a 33-year old man who disclosed the first case of bilateral ocular involvement of hand, foot, and mouth disease (HFMD) with a different stage of the disease in each eye. Methods: Retrospective case report. Results: The study included a patient who incurred in a bilateral HFMD maculopathy. During 6 months follow-up period persistent abnormalities in fundus examination and in OCT scans were reported. Conclusion: We consider that our case shows that choriocapillaris is the primary target of HFMD maculopathy, for this reason we consider that ICGA is mandatory for early diagnosis and an effective treatment.

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Susac's syndrome: the first case report in a Nordic country, with an 8-year follow-up

Acta Ophthalmologica Scandinavica ◽

10.1111/j.1600-0420.2005.00558.x ◽

2005 ◽

Vol 83 (6) ◽

pp. 757-758 ◽

Cited By ~ 4

Author(s):

Nicolai Gruhn ◽

Line Kynemund Pedersen ◽

Niels Vesti Nielsen

Keyword(s):

Case Report ◽

Nordic Country ◽

Susac’S Syndrome ◽

First Case

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Metastasis from Penile Squamous Cell Carcinoma to Brain: A Case Report and Review of Literature

Indian Journal of Neurosurgery ◽

10.1055/s-0037-1601359 ◽

2017 ◽

Vol 07 (02) ◽

pp. 164-167

Author(s):

Hanish Bansal ◽

Ashwani Chaudhary ◽

Dipesh Batra ◽

Rohit Jindal

Keyword(s):

Squamous Cell Carcinoma ◽

Case Report ◽

Brain Metastasis ◽

Literature Review ◽

Rare Case ◽

Systemic Disease ◽

Penile Carcinoma ◽

Review Of Literature ◽

Penile Squamous Cell Carcinoma

AbstractWe report a very rare case of a 63-year-old man with penile carcinoma who developed brain metastasis. Brain metastasis from penile carcinoma is very rare, and only six cases have been reported so far as per our literature review. In view of controlled primary tumor and absence of systemic disease, tumor was excised and the patient remained clinically controlled till 3 months after follow-up.

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Citalopram intoxication in four week old infant

BMC Pediatrics ◽

10.1186/s12887-020-02439-5 ◽

2020 ◽

Vol 20 (1) ◽

Cited By ~ 1

Author(s):

Jo-Anne Janson ◽

Arthur T. M. Wasylewicz ◽

Marianne Eijkemans ◽

Marieke Kerskes

Keyword(s):

Case Report ◽

Cardiac Rhythm ◽

Clinical Course ◽

Screening Methods ◽

Pharmacokinetic Data ◽

Pediatric Practice ◽

Case Presentation ◽

Young Infants ◽

First Case

Abstract Background In contrast to intoxications in toddlers which can be due to accidental ingestions, many intoxications in infants are due to medication errors. To our knowledge, this is the first case report of a citalopram intoxication in an infant, and may offer new insight on possible screening methods for intoxication as well as pharmacokinetics of citalopram in small infants. Case presentation This case report describes an unintentional citalopram intoxication in a 4 week old infant due to a vitamin D drops ‘look alike’ error. The infant showed extreme jitteriness and opisthotonus at presentation, as well as prolonged signs of gastro-oesophageal reflux. No cardiac rhythm disturbances or convulsions were seen. The clinical course combined with Finnegan scores was correlated to and supported by pharmacokinetic and pharmacokinetic data of citalopram in the patient. Conclusions Using Finnegan scores in general pediatric practice could help objectify follow-up of acute intoxications in young infants with neurological symptoms.

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A case report of wireless peripheral nerve stimulation for complex regional pain syndrome type-I of the upper extremity: 1 year follow up

Scandinavian Journal of Pain ◽

10.1515/sjpain-2019-0071 ◽

2019 ◽

Vol 19 (4) ◽

pp. 829-835 ◽

Cited By ~ 1

Author(s):

Daniel Herschkowitz ◽

Jana Kubias

Keyword(s):

Case Report ◽

Minimally Invasive ◽

Peripheral Nerve ◽

Upper Extremity ◽

Nerve Stimulation ◽

Pain Syndrome ◽

Peripheral Nerve Stimulation ◽

Type I ◽

First Case

Abstract Background Complex regional pain syndrome (CRPS) is a chronic disabling painful disorder with limited options to achieve therapeutic relief. CRPS type I which follows trauma, may not show obvious damage to the nervous structures and remains dubious in its pathophysiology and also its response to conservative treatment or interventional pain management is elusive. Spinal cord and dorsal root ganglion stimulation (SCS, DRGS) provide good relief, mainly for causalgia or CRPS I of lower extremities but not very encouraging for upper extremity CRPS I. we reported earlier, a case of CRPS I of right arm treated successfully by wireless peripheral nerve stimulation (WPNS) with short term follow up. Here we present 1-year follow-up of this patient. Objective To present the first case of WPNS for CRPS I with a year follow up. The patient had minimally invasive peripheral nerve stimulation (PNS), without implantable pulse generator (IPG) or its accessories. Case report This was a case of refractory CRPS I after blunt trauma to the right forearm of a young female. She underwent placement of two Stimwave electrodes (Leads: FR4A-RCV-A0 with tines, Generation 1 and FR4A-RCV-B0 with tines, Generation 1) in her forearm under intraoperative electrophysiological and ultrasound guidance along radial and median nerves. This WPNS required no IPG. At high frequency (HF) stimulation (HF 10 kHz/32 μs, 2.0 mA), patient had shown remarkable relief in pain, allodynia and temperature impairment. At 5 months she started driving without opioid consumption, while allodynia disappeared. At 1 year follow up she was relieved of pain [visual analogue scale (VAS) score of 4 from 7] and Kapanji Index (Score) improved to 7–8. Both hands look similar in color and temperature. She never made unscheduled visits to the clinic or visited emergency room for any complications related to the WPNS. Conclusions CRPS I involving upper extremity remain difficult to manage with conventional SCS or DRGS because of equipment related adverse events. Minimally invasive WPNS in this case had shown consistent relief without any complications or side effects related to the wireless technology or the technique at the end of 1 year. Implications This is the first case illustration of WPNS for CRPS I, successfully treated and followed up for 1 year.

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